Autism spectrum symptoms in Smith-Magenis syndrome and Williams syndrome: comparisons and contrasts

dc.contributor.authorOsório, Ana Alexandra Caldaspor
dc.contributor.authorSampaio, Adrianapor
dc.contributor.authorMartínez Regueiro, Rocíopor
dc.contributor.authorGarayzábal Heinze, Elenapor
dc.contributor.authorCarracedo, Ángelpor
dc.contributor.authorFernández Prieto, Montsepor
dc.date.accessioned2021-04-16T13:58:10Z
dc.date.embargo10000-01-01
dc.date.issued2015-01
dc.date.updated2021-04-15T17:14:59Z
dc.description.abstractObjectives: Genetic syndromes with distinctive cognitive and behavioural phenotypes - such as Smith-Magenis syndrome (SMS) and Williams syndrome (WS) - offer unique opportunities to explore the links between specific genes and neurodevelopmental disorders. While some studies have reported the occurrence of autistic symptoms in SMS, evidence for such symptomatology in WS is scarcer. This study is the first to compare and contrast levels of autistic symptoms in SMS and WS.Methods: Parents/caregivers of 11 individuals with SMS and 14 individuals with WS completed the Social Communication Questionnaire.Results: Results indicate that both syndromes present, albeit in distinct degrees, behavioural signs of the autistic spectrum. The SMS group scored significantly higher on both current and lifetime symptoms. The mean lifetime form score of the SMS group (particularly males) was consonant with the presence of an autism spectrum disorder. Regarding the WS group, even though the mean score was below the clinical threshold, it was still above what has been reported in typically developing samples.Conclusion: Our study contributes to a better definition of the neurobehavioural profiles of SMS and WS, as it offers comparisons and contrasts that may, in turn, prove beneficial for early diagnosis and intervention.por
dc.description.sponsorshipThis research was supported by FEDER funds through the Competitive Factors Operational Programme — COMPETE, by national funds from the Portuguese Foundation for Science and Technology (grant PTDC/PSI-PCL/115316/2009) and by Fundación Alicia Koplowitz (Fifth Call for grants for Research in Childhood and Adolescent Psychiatry Early Neurodegenerative Diseases).por
dc.distributioninternationalpor
dc.identifier.doi10.1179/2047387713Y.0000000035por
dc.identifier.eissn2047-3877por
dc.identifier.issn2047-3869por
dc.identifier.urihttps://hdl.handle.net/1822/71982
dc.language.isoengpor
dc.peerreviewedyespor
dc.publisherTaylor & Francispor
dc.relationinfo:eu-repo/grantAgreement/FCT/5876-PPCDTI/115316/PTpor
dc.relation.publisherversionhttps://www.tandfonline.com/doi/abs/10.1179/2047387713Y.0000000035por
dc.rightsrestrictedAccesspor
dc.subjectSmith-Magenis syndromepor
dc.subjectWilliams syndromepor
dc.subjectAutistic symptomspor
dc.subject.wosSocial Sciences
dc.subject.wosScience & Technology
dc.titleAutism spectrum symptoms in Smith-Magenis syndrome and Williams syndrome: comparisons and contrastspor
dc.typearticle
dspace.entity.typePublicationen
oaire.citationEndPage55por
oaire.citationIssue1por
oaire.citationStartPage49por
oaire.citationVolume61por
sdum.export.identifier10650
sdum.journalInternational Journal of Developmental Disabilitiespor

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